A 27-year-old woman presented with ectopic recurrence manifesting as an asymptomatic mass in the left frontal convexity 5 years after subtotal removal of suprasellar craniopharyngioma through a right orbitozygomatic craniotomy. The mass had enlarged gradually over the next 5 years, so a second operation was performed for total removal. The histological diagnoses of both lesions were adamantinomatous type craniopharyngioma with MIB-1 indexes of 4.2% and 7.4%. The second lesion probably resulted from dissemination. Craniopharyngioma is a benign tumor, and ectopic recurrence is rare. Long-term clinical and neuroimaging follow up is recommended.