Skip to main content
Erschienen in: Rheumatology International 11/2019

09.09.2019 | Cases with a Message

Microsporidial myositis in adult-onset immunodeficiency: case-based review

verfasst von: T. G. Sundaram, Amita Aggarwal, Sujata Ganguly, Elgiva Khristie Iangngap, Rungmei S. K. Marak, Latika Gupta

Erschienen in: Rheumatology International | Ausgabe 11/2019

Einloggen, um Zugang zu erhalten

Abstract

Polymyositis is a diagnosis of exclusion. In patients with odd features, it can be of infective etiology. A high index of suspicion is required for diagnosis. A 55-year-old gentleman presented with gradual-onset proximal muscle weakness. Examination revealed mild distal weakness but no rash. Muscle enzymes were raised and tests for autoantibodies were negative. Biopsy revealed microsporidiosis. In view of this unusual infection, immunodeficiency was considered and he was found to have lymphopenia which antedated his illness. Later, he developed cranial nerve palsies due to multiple lesions in the pons. In addition, he had Cytomegalovirus viremia. Literature was reviewed to identify 20 cases of microsporidial myositis, its presentation, underlying immunodeficient state, and clinical course. Infective polymyositis should be considered in a patient with paucity of clinical and serological autoimmune features. Lymphopenia can point to underlying immunodeficiency. CMV infection could be the contributor to or bystander-effect of idiopathic lymphopenia.
Literatur
1.
Zurück zum Zitat John J (1984) Grading of muscle power: comparison of MRC and analogue scales by physiotherapists. Medical Research Council. Int J Rehabil Res 7:173–181CrossRef John J (1984) Grading of muscle power: comparison of MRC and analogue scales by physiotherapists. Medical Research Council. Int J Rehabil Res 7:173–181CrossRef
2.
Zurück zum Zitat Kendall FP, McCreary EK, Provance PG (1993) Muscles: testing and function, 4th edn. Williams and Wilkins, Baltimore Kendall FP, McCreary EK, Provance PG (1993) Muscles: testing and function, 4th edn. Williams and Wilkins, Baltimore
3.
Zurück zum Zitat Gasparyan AY, Ayvazyan L, Blackmore H, Kitas GD (2011) Writing a narrative biomedical review: considerations for authors, peer reviewers, and editors. Rheumatol Int 31:1409–1417CrossRef Gasparyan AY, Ayvazyan L, Blackmore H, Kitas GD (2011) Writing a narrative biomedical review: considerations for authors, peer reviewers, and editors. Rheumatol Int 31:1409–1417CrossRef
4.
Zurück zum Zitat Preston DC (1993) Electrophysiology of microsporidia myositis in an AIDS patient. Muscle Nerve 16:1420–1422PubMed Preston DC (1993) Electrophysiology of microsporidia myositis in an AIDS patient. Muscle Nerve 16:1420–1422PubMed
5.
Zurück zum Zitat Grau A, Valls ME, Williams JE, Ellis DS, Muntané MJ, Nadal C (1996) Myositis caused by Pleistophora in a patient with AIDS. Med Clin (Barc) 107:779–781 Grau A, Valls ME, Williams JE, Ellis DS, Muntané MJ, Nadal C (1996) Myositis caused by Pleistophora in a patient with AIDS. Med Clin (Barc) 107:779–781
6.
Zurück zum Zitat Margileth AM, Strano AJ, Chandra R, Neafie R, Blum M, McCully RM (1973) Disseminated nosematosis in an immunologically compromised infant. Arch Pathol 95:145–150PubMed Margileth AM, Strano AJ, Chandra R, Neafie R, Blum M, McCully RM (1973) Disseminated nosematosis in an immunologically compromised infant. Arch Pathol 95:145–150PubMed
7.
Zurück zum Zitat Ledford DK, Overman MD, Gonzalvo A et al (1985) Microsporidiosis myositis in a patient with the acquired immunodeficiency syndrome. Ann Intern Med 102:628–630CrossRef Ledford DK, Overman MD, Gonzalvo A et al (1985) Microsporidiosis myositis in a patient with the acquired immunodeficiency syndrome. Ann Intern Med 102:628–630CrossRef
8.
Zurück zum Zitat Cali A, Takvorian PM (2003) Ultrastructure and development of Pleistophora ronneafiei n. sp., a Microsporidium (Protista) in the skeletal muscle of an immune-compromised individual. J Eukaryot Microbiol 50:77–85CrossRef Cali A, Takvorian PM (2003) Ultrastructure and development of Pleistophora ronneafiei n. sp., a Microsporidium (Protista) in the skeletal muscle of an immune-compromised individual. J Eukaryot Microbiol 50:77–85CrossRef
9.
Zurück zum Zitat Macher AM, Neafie R, Angritt P, Tuur SM (1988) Microsporidial myositis and the acquired immunodeficiency syndrome (AIDS): a four-year follow-up. Ann Intern Med 109:343CrossRef Macher AM, Neafie R, Angritt P, Tuur SM (1988) Microsporidial myositis and the acquired immunodeficiency syndrome (AIDS): a four-year follow-up. Ann Intern Med 109:343CrossRef
10.
Zurück zum Zitat Chupp GL, Alroy J, Adelman LS, Breen JC, Skolnik PR (1993) Myositis due to Pleistophora (Microsporidia) in a patient with AIDS. Clin Infect Dis 16:15–21CrossRef Chupp GL, Alroy J, Adelman LS, Breen JC, Skolnik PR (1993) Myositis due to Pleistophora (Microsporidia) in a patient with AIDS. Clin Infect Dis 16:15–21CrossRef
11.
Zurück zum Zitat Cali A, Takvorian PM, Lewin S, Rendel M, Sian C, Wittner M, Weiss LM (1996) Identification of a new Nosema-like microsporidian associated with myositis in an AIDS patient. J Eukaryot Microbiol 43:108SCrossRef Cali A, Takvorian PM, Lewin S, Rendel M, Sian C, Wittner M, Weiss LM (1996) Identification of a new Nosema-like microsporidian associated with myositis in an AIDS patient. J Eukaryot Microbiol 43:108SCrossRef
12.
Zurück zum Zitat Field AS, Marriott DJ, Milliken ST, Brew BJ, Canning EU, Kench JG, Darveniza P, Harkness JL (1996) Myositis associated with a newly described microsporidian, Trachipleistophora hominis, in a patient with AIDS. J Clin Microbiol 34:2803–2811CrossRef Field AS, Marriott DJ, Milliken ST, Brew BJ, Canning EU, Kench JG, Darveniza P, Harkness JL (1996) Myositis associated with a newly described microsporidian, Trachipleistophora hominis, in a patient with AIDS. J Clin Microbiol 34:2803–2811CrossRef
13.
Zurück zum Zitat Cali A et al (1998) Brachiola vesicularum, n. g., n. sp., a new microsporidium associated with AIDS and myositis. J Eukaryot Microbiol 45:240–251CrossRef Cali A et al (1998) Brachiola vesicularum, n. g., n. sp., a new microsporidium associated with AIDS and myositis. J Eukaryot Microbiol 45:240–251CrossRef
14.
Zurück zum Zitat Coyle CM et al (2004) Fatal myositis due to the microsporidian Brachiola algerae, a mosquito pathogen. N Engl J Med 351:42–47CrossRef Coyle CM et al (2004) Fatal myositis due to the microsporidian Brachiola algerae, a mosquito pathogen. N Engl J Med 351:42–47CrossRef
15.
Zurück zum Zitat Curry A, Beeching NJ, Gilbert JD, Scott G, Rowland PL, Currie BJ (2005) Trachipleistophora hominis infection in the myocardium and skeletal muscle of a patient with AIDS. J Infect 51:e139–e144CrossRef Curry A, Beeching NJ, Gilbert JD, Scott G, Rowland PL, Currie BJ (2005) Trachipleistophora hominis infection in the myocardium and skeletal muscle of a patient with AIDS. J Infect 51:e139–e144CrossRef
16.
Zurück zum Zitat Choudhary MM et al (2011) Tubulinosema sp. microsporidian myositis in immunosuppressed patient. Emerg Infect Dis 17:1727–1730CrossRef Choudhary MM et al (2011) Tubulinosema sp. microsporidian myositis in immunosuppressed patient. Emerg Infect Dis 17:1727–1730CrossRef
17.
Zurück zum Zitat Suankratay C, Thiansukhon E, Nilaratanakul V, Putaporntip C, Jongwutiwes S (2012) Disseminated infection caused by novel species of Microsporidium, Thailand. Emerg Infect Dis 18:302–304CrossRef Suankratay C, Thiansukhon E, Nilaratanakul V, Putaporntip C, Jongwutiwes S (2012) Disseminated infection caused by novel species of Microsporidium, Thailand. Emerg Infect Dis 18:302–304CrossRef
18.
Zurück zum Zitat Field AS et al (2012) Myositis due to the microsporidian Anncaliia (Brachiola) algerae in a lung transplant recipient. Transpl Infect Dis 14:169–176CrossRef Field AS et al (2012) Myositis due to the microsporidian Anncaliia (Brachiola) algerae in a lung transplant recipient. Transpl Infect Dis 14:169–176CrossRef
19.
Zurück zum Zitat Watts MR et al (2014) Anncaliia algerae microsporidial myositis. Emerg Infect Dis 20:185–191CrossRef Watts MR et al (2014) Anncaliia algerae microsporidial myositis. Emerg Infect Dis 20:185–191CrossRef
20.
Zurück zum Zitat Patel AK et al (2015) Microsporidial polymyositis in human immunodeficiency virus-infected patients, a rare life-threatening opportunistic infection: clinical suspicion, diagnosis, and management in resource-limited settings. Muscle Nerve 51:775–780CrossRef Patel AK et al (2015) Microsporidial polymyositis in human immunodeficiency virus-infected patients, a rare life-threatening opportunistic infection: clinical suspicion, diagnosis, and management in resource-limited settings. Muscle Nerve 51:775–780CrossRef
21.
Zurück zum Zitat Boileau M et al (2016) Successful treatment of disseminated Anncaliia algerae microsporidial infection with combination fumagillin and albendazole. Open Forum Infect Dis 3:ofw158CrossRef Boileau M et al (2016) Successful treatment of disseminated Anncaliia algerae microsporidial infection with combination fumagillin and albendazole. Open Forum Infect Dis 3:ofw158CrossRef
22.
Zurück zum Zitat Sutrave G et al (2018) Anncaliia algerae microsporidial myositis, New South Wales, Australia. Emerg Infect Dis 24:1528–1531CrossRef Sutrave G et al (2018) Anncaliia algerae microsporidial myositis, New South Wales, Australia. Emerg Infect Dis 24:1528–1531CrossRef
24.
Zurück zum Zitat Williams BA, Hirt RP, Lucocq JM, Embley TM (2001) A mitochondrial remnant in the microsporidian Trachipleistophora hominis. Nature 418:865–869CrossRef Williams BA, Hirt RP, Lucocq JM, Embley TM (2001) A mitochondrial remnant in the microsporidian Trachipleistophora hominis. Nature 418:865–869CrossRef
25.
Zurück zum Zitat Weiss LM, Becnel JJ (2014) Microsporidia: pathogens of opportunity. Blackwell, OxfordCrossRef Weiss LM, Becnel JJ (2014) Microsporidia: pathogens of opportunity. Blackwell, OxfordCrossRef
26.
Zurück zum Zitat Saigal K, Sharma A, Sehgal R et al (2013) Intestinal microsporidiosis in India: a two-year study. Parasitol Int 62:53–56CrossRef Saigal K, Sharma A, Sehgal R et al (2013) Intestinal microsporidiosis in India: a two-year study. Parasitol Int 62:53–56CrossRef
27.
Zurück zum Zitat Field AS, Milner DA Jr (2015) Intestinal microsporidiosis. Clin Lab Med 35:445–459CrossRef Field AS, Milner DA Jr (2015) Intestinal microsporidiosis. Clin Lab Med 35:445–459CrossRef
28.
Zurück zum Zitat Ramanan P, Pritt BS (2014) Extraintestinal microsporidiosis. J Clin Microbiol 52:3839–3844CrossRef Ramanan P, Pritt BS (2014) Extraintestinal microsporidiosis. J Clin Microbiol 52:3839–3844CrossRef
29.
Zurück zum Zitat Cheney SA, Lafranchi-Tristem NJ, Canning EU (2000) Phylogenetic relationships of Pleistophora-like microsporidia based on small subunit ribosomal DNA sequences and implications for the source of Trachipleistophora hominis infections. J Eukaryot Microbiol 47:280–287CrossRef Cheney SA, Lafranchi-Tristem NJ, Canning EU (2000) Phylogenetic relationships of Pleistophora-like microsporidia based on small subunit ribosomal DNA sequences and implications for the source of Trachipleistophora hominis infections. J Eukaryot Microbiol 47:280–287CrossRef
30.
Zurück zum Zitat Herbinger KH et al (2016) A controlled cross-sectional study of 17,229 diseased German travelers returning from the tropics and subtropics. Am J Trop Med Hyg 94:1385–1391CrossRef Herbinger KH et al (2016) A controlled cross-sectional study of 17,229 diseased German travelers returning from the tropics and subtropics. Am J Trop Med Hyg 94:1385–1391CrossRef
31.
Zurück zum Zitat Parasca I, Damian L, Albu A (2006) Infectious muscle disease. Rom J Intern Med 44:131–141PubMed Parasca I, Damian L, Albu A (2006) Infectious muscle disease. Rom J Intern Med 44:131–141PubMed
32.
Zurück zum Zitat Borges IBP, Silva MG, Misse RG, Shinjo SK (2018) Lipid-lowering agent-triggered dermatomyositis and polymyositis: a case series and literature review. Rheumatol Int 38:293–301CrossRef Borges IBP, Silva MG, Misse RG, Shinjo SK (2018) Lipid-lowering agent-triggered dermatomyositis and polymyositis: a case series and literature review. Rheumatol Int 38:293–301CrossRef
33.
Zurück zum Zitat Perricone C, Colafrancesco S, Mazor RD, Soriano A, Agmon-Levin N, Shoenfeld Y (2013) Autoimmune/inflammatory syndrome induced by adjuvants (ASIA): unveiling the pathogenic, clinical and diagnostic aspects. J Autoimmun 47:1–16CrossRef Perricone C, Colafrancesco S, Mazor RD, Soriano A, Agmon-Levin N, Shoenfeld Y (2013) Autoimmune/inflammatory syndrome induced by adjuvants (ASIA): unveiling the pathogenic, clinical and diagnostic aspects. J Autoimmun 47:1–16CrossRef
Metadaten
Titel
Microsporidial myositis in adult-onset immunodeficiency: case-based review
verfasst von
T. G. Sundaram
Amita Aggarwal
Sujata Ganguly
Elgiva Khristie Iangngap
Rungmei S. K. Marak
Latika Gupta
Publikationsdatum
09.09.2019
Verlag
Springer Berlin Heidelberg
Erschienen in
Rheumatology International / Ausgabe 11/2019
Print ISSN: 0172-8172
Elektronische ISSN: 1437-160X
DOI
https://doi.org/10.1007/s00296-019-04439-w

Weitere Artikel der Ausgabe 11/2019

Rheumatology International 11/2019 Zur Ausgabe

Leitlinien kompakt für die Innere Medizin

Mit medbee Pocketcards sicher entscheiden.

Seit 2022 gehört die medbee GmbH zum Springer Medizin Verlag

Update Innere Medizin

Bestellen Sie unseren Fach-Newsletter und bleiben Sie gut informiert.